DOI: https://doi.org/10.36347/sjmcr.2025.v13i03.048

Pages: 527-529

Female hypospadias (FH) is an extremely rare congenital anomaly characterized by an abnormally located urethral meatus on the anterior vaginal wall. Unlike male hypospadias, FH is seldom observed and is often overlooked, typically coexisting with other urogenital anomalies. The primary treatment is surgical urethral reconstruction. We present the case of a 26-year-old woman with a history of congenital adrenal hyperplasia and female pseudohermaphroditism. During an infertility work-up, a pelvic MRI revealed a urethro-vaginal communication concurrent with FH.