DOI: https://doi.org/10.36347/sjmcr.2025.v13i05.026

Pages: 879-881

Testicular Adrenal Rest Tumors (ISIT) are rare benign tumors observed in hormone adrénocorticotrope hypersecretion syndromes, particularly in congenital adrenal hyperplasia (CAH). They originate from aberrant adrenal cortical cells that descend with the testes during embryogenesis. It is the most common cause of infertility in adult men. The diagnosis relies on ultrasound and histological criteria, which help distinguish them from Leydig cell tumors. We report the case of bilateral TARTs in patient with CAH due to a 21-hydroxylase enzyme deficiency. The testicular ultrasound revealed multiple bilateral testicular nodular formations measuring 32*20*38.6 mm on the right and 40*24.4*54 mm on the left, compatible with the diagnosis of TARTs. The patient was treated with a suppressive glucocorticoids 1 mg of Dexamethasone daily. The early detection of TARTs in men with CAH enables timely interventions to preserve fertility before testicular function declines.